Journal of Medical Genetics - 2007

164 articles | Last updated: 2025-12-03 14:12:57
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Article Title Cauc. White Euro. Other Phrases Used
T A T A T A T A
Duplication of the Williams-Beuren critical region: case report and further delineation of the phenotypic spectrum
The facial dysmorphy in the newly recognised microdeletion 2p15-p16.1 refined to a 570 kb region in 2p15
"SCA16" is really SCA15
Molecular analysis of digenic inheritance in Bartter syndrome with sensorineural deafness
Isolated cytochrome c oxidase deficiency as a cause of MELAS
A newly recognised microdeletion syndrome involving 2p15p16.1: narrowing down the critical region by adding another patient detected by genome wide tiling path array comparative genomic hybridisation
Estimating risks of common complex diseases: familial and population risks
Human Gene Mutation Database: towards a comprehensive central mutation database
SCN5A R1193Q polymorphism associated with progressive cardiac conduction defects and long QT syndrome in a Chinese family Chinese
Correction
Further pitfalls in the diagnosis of mtDNA mutations: homoplasmic mt-tRNA mutations
Diversity of the basic defect of homozygous CFTR mutation genotypes in humans
BRCA2: a cause of Li Fraumeni-like syndrome
Is CHEK2 a cause of the Li Fraumeni syndrome?
The genetic aetiology of Silver-Russell syndrome
Evidence for the association of Y-chromosome haplogroups with susceptibility to spermatogenic failure in a Chinese Han population
Myosin IXB gene region and gluten intolerance: linkage to coeliac disease and a putative dermatitis herpetiformis association
Genetic risk for myocardial infarction determined by polymorphisms of candidate genes in a Japanese population
A patient with vertebral, cognitive and behavioural abnormalities and a de novo deletion of NRXN1 
A low symptomatic form of neurodegeneration in younger carriers of the FMR1 premutation, manifesting typical radiological changes
Molecular characterisation of a common SDHB deletion in paraganglioma patients
 7 Nicotinic acetylcholine receptor gene and reduced risk of Alzheimer's disease
Episodic ataxia and hemiplegia caused by the 8993T->C mitochondrial DNA mutation
GATA4 sequence variants in patients with congenital heart disease
Deletions of NF1 gene and exons detected by multiplex ligation-dependent probe amplification
Severe neonatal manifestations of Costello syndrome
Further delineation of cardio-facio-cutaneous syndrome: clinical features of 38 individuals with proven mutations
Genomic imbalances associated with mullerian aplasia
Duplications in addition to terminal deletions are present in a proportion of ring chromosomes: clues to the mechanisms of formation
A novel connexin50 mutation associated with congenital nuclear pulverulent cataracts
A novel missense mutation in GJB2 disturbs gap junction protein transport and causes focal palmoplantar keratoderma with deafness
Impairment of CDKL5 nuclear localisation as a cause for severe infantile encephalopathy
Psoriasis is associated with pleiotropic susceptibility loci identified in type II diabetes and Crohn disease
Spectrum, and clinical and functional implications of UNC13D mutations in familial haemophagocytic lymphohistiocytosis
Age and origin of major Smith-Lemli-Opitz syndrome (SLOS) mutations in European populations European populations
Hirschsprung disease, associated syndromes and genetics: a review
Polymorphic MLH1 and risk of cancer after methylating chemotherapy for Hodgkin lymphoma
A novel mitochondrial ATP8 gene mutation in a patient with apical hypertrophic cardiomyopathy and neuropathy
Methylation-specific multiplex ligation-dependent probe amplification (MS-MLPA) robustly detects and distinguishes 11p15 abnormalities associated with overgrowth and growth retardation
Correction
The T/G 13915 variant upstream of the lactase gene (LCT) is the founder allele of lactase persistence in an urban Saudi population
Assignment of two loci for autosomal dominant adolescent idiopathic scoliosis to chromosomes 9q31.2-q34.2 and 17q25.3-qtel
Deletion of a 760 kb region at 4p16 determines the prenatal and postnatal growth retardation characteristic of Wolf-Hirschhorn syndrome
Salbutamol increases SMN mRNA and protein levels in spinal muscular atrophy cells
ARHGEF9 disruption in a female patient is associated with X linked mental retardation and sensory hyperarousal
General mutation databases: analysis and review
Clinical spectrum of immunodeficiency, centromeric instability and facial dysmorphism (ICF syndrome)
Heterozygous deletion of ITPR1, but not SUMF1, in spinocerebellar ataxia type 16
Dissection of the aorta in Turner syndrome: two cases and review of 85 cases in the literature
Identification of novel candidate genes associated with cleft lip and palate using array comparative genomic hybridisation
High proportion of large genomic deletions and a genotype phenotype update in 80 unrelated families with juvenile polyposis syndrome
Genotype-phenotype correlation in 21 patients with Wolf-Hirschhorn syndrome using high resolution array comparative genome hybridisation (CGH)
Antenatal mitochondrial disease caused by mitochondrial ribosomal protein (MRPS22) mutation
Genotype phenotype study of familial haemophagocytic lymphohistiocytosis due to perforin mutations
Genetic risk for metabolic syndrome: examination of candidate gene polymorphisms related to lipid metabolism in Japanese people
Cryptic deletions are a common finding in "balanced" reciprocal and complex chromosome rearrangements: a study of 59 patients
New PPARG mutation leads to lipodystrophy and loss of protein function that is partially restored by a synthetic ligand
Rare heterozygous parkin variants in French early-onset Parkinson disease patients and controls
Molecular pathogenesis of Wilson and Menkes disease: correlation of mutations with molecular defects and disease phenotypes
Cardio-facio-cutaneous and Noonan syndromes due to mutations in the RAS/MAPK signalling pathway: genotype phenotype relationships and overlap with Costello syndrome
Gender-stratified analysis of DLG5 R30Q in 4707 patients with Crohn disease and 4973 controls from 12 Caucasian cohorts
Clinical, molecular and histopathological features of short stature syndrome with novel CUL7 mutation in Yakuts: new population isolate in Asia
Deletions or duplications in KCNQ2 can cause benign familial neonatal seizures
Correction
Response to correspondence on "Phenocopies in BRCA1 and BRCA2 families: evidence for modifier genes and implications for screening"
A genome-wide scan for genes involved in primary vesicoureteric reflux
Blood-derived gene-expression profiling in unravelling susceptibility to recessive disease
Estimating risks of common complex diseases across genetic and environmental factors: the example of Crohn disease
A novel hearing loss-related mutation occurring in the GJB2 basal promoter
Germline E-cadherin mutations in familial lobular breast cancer
Factors associated with HD CAG repeat instability in Huntington disease
Raised risk of Wilms tumour in patients with aniridia and submicroscopic WT1 deletion
Direct contact in inviting high-risk members of hereditary colon cancer families to genetic counselling and DNA testing
Isolated imprinting mutation of the DLK1/GTL2 locus associated with a clinical presentation of maternal uniparental disomy of chromosome 14
Molecular karyotyping in patients with mental retardation using 100K single-nucleotide polymorphism arrays
CORRECTION
Familial T-cell non-Hodgkin lymphoma caused by biallelic MSH2 mutations
Mutation of the gap junction protein alpha 8 (GJA8) gene causes autosomal recessive cataract
De novo HRAS and KRAS mutations in two siblings with short stature and neuro-cardio-facio-cutaneous features
The C20orf133 gene is disrupted in a patient with Kabuki syndrome
SOS1 is the second most common Noonan gene but plays no major role in cardio-facio-cutaneous syndrome
Mutation analysis of NPHP6/CEP290 in patients with Joubert syndrome and Senior Loken syndrome
Mutations in the AP1S2 gene encoding the sigma 2 subunit of the adaptor protein 1 complex are associated with syndromic X-linked mental retardation with hydrocephalus and calcifications in basal gangl
Mutation detection in the ABCC6 gene and genotype phenotype analysis in a large international case series affected by pseudoxanthoma elasticum
Congenital ichthyosis: mutations in ichthyin are associated with specific structural abnormalities in the granular layer of epidermis
Genetic screening for pheochromocytoma: should SDHC gene analysis be included?
Genetic association analysis of inositol polyphosphate phosphatase-like 1 (INPPL1, SHIP2) variants with essential hypertension
The IRF5 polymorphism in type 1 diabetes
Different CTNNB1 mutations as molecular genetic proof for the independent origin of four Wilms tumours in a patient with a novel germ line WT1 mutation
Phenocopies in families seen by cancer geneticists
Pierre Robin sequence may be caused by dysregulation of SOX9 and KCNJ2
CORRECTION
Mitochondrial DNA haplogroups and type 2 diabetes: a study of 897 cases and 1010 controls
Should healthcare providers have a duty to warn family members of individuals with an HNPCC-causing mutation? A survey of patients from the Ontario Familial Colon Cancer Registry
Autosomal recessive postlingual hearing loss (DFNB8): compound heterozygosity for two novel TMPRSS3 mutations in German siblings German
Novel deletions of 14q11.2 associated with developmental delay, cognitive impairment and similar minor anomalies in three children
Stability of the m.8993T->G mtDNA mutation load during human embryofetal development has implications for the feasibility of prenatal diagnosis in NARP syndrome
The spectrum of vascular anomalies in patients with PTEN mutations: implications for diagnosis and management
Cowden syndrome and Bannayan Riley Ruvalcaba syndrome represent one condition with variable expression and age-related penetrance: results of a clinical study of PTEN mutation carriers
Cargos and genes: insights into vesicular transport from inherited human disease
Correlations between clinical severity, genotype and muscle pathology in limb girdle muscular dystrophy type 2A
The novel IFNGR1 mutation 774del4 produces a truncated form of interferon-  receptor 1 and has a dominant-negative effect on interferon-  signal transduction
Contribution of the N-acetyltransferase 2 polymorphism NAT2*6A to age-related hearing impairment
A functional CD86 polymorphism associated with asthma and related allergic disorders
Coordinated transcriptional regulation patterns associated with infertility phenotypes in men
Mutations of the Birt Hogg Dube gene in patients with multiple lung cysts and recurrent pneumothorax
Insulin-degrading enzyme is genetically associated with Alzheimer's disease in the Finnish population Finnish population
Pregnancy does not influence colonic polyp multiplicity but may modulate upper gastrointestinal disease in patients with FAP
Differences in ATP7A gene expression underlie intrafamilial variability in Menkes disease/occipital horn syndrome
Biallelic mutation of MSH2 in primary human cells is associated with sensitivity to irradiation and altered RAD51 foci kinetics
Unexplained autism is frequently associated with low-level mosaic aneuploidy
Phenotypic diversity of Menkes disease in mottled mice is associated with defects in localisation and trafficking of the ATP7A protein
Genotype phenotype correlation of 30 patients with Smith-Magenis syndrome (SMS) using comparative genome hybridisation array: cleft palate in SMS is associated with larger deletions
FRA18C: a new aphidicolin-inducible fragile site on chromosome 18q22, possibly associated with in vivo chromosome breakage
Exon skipping through the creation of a putative exonic splicing silencer as a consequence of the cystic fibrosis mutation R553X
No screening yet after a negative test for the family mutation
L-2-hydroxyglutaric aciduria: characterisation of the molecular defect in a spontaneous canine model
Myopathy caused by HRAS germline mutations: implications for disturbed myogenic differentiation in the presence of constitutive HRas activation
Connexin 50 gene on human chromosome 1q21 is associated with schizophrenia in matched case control and family-based studies
Attenuated aerobic exercise capacity in CD36 deficiency
Correction
Partial deletions are associated with an increased risk of complete deletion in AZFc: a new insight into the role of partial AZFc deletions in male infertility
Correction
Autism, language delay and mental retardation in a patient with 7q11 duplication
The Shwachman-Bodian-Diamond syndrome gene mutations cause a neonatal form of spondylometaphysial dysplasia (SMD) resembling SMD Sedaghatian type
Mutations in the ND5 subunit of complex I of the mitochondrial DNA are a frequent cause of oxidative phosphorylation disease
Array comparative genomic hybridisation analysis of boys with X-linked hypopituitarism identifies a 3.9 Mb duplicated critical region at Xq27 containing SOX3
A survey of locus-specific database curation
Hypomethylation in the 11p15 telomeric imprinting domain in a patient with Silver-Russell syndrome with a CSH1 deletion (17q24) renders a functional role of this alteration unlikely
Phenocopies in breast cancer 1 (BRCA1) families: implications for genetic counselling
Women with neurofibromatosis 1 are at a moderately increased risk of developing breast cancer and should be considered for early screening
Association of arginase 1 gene polymorphisms with the risk of myocardial infarction and common carotid intima media thickness
The original Lujan syndrome family has a novel missense mutation (p.N1007S) in the MED12 gene
MECP2 mutations in males
Cleft lip with or without cleft palate: implication of the heavy chain of non-muscle myosin IIA
Analysis of sex chromosome abnormalities using X and Y chromosome DNA tiling path arrays
Further evidence of the increased risk for malignant peripheral nerve sheath tumour from a Scottish cohort of patients with neurofibromatosis type 1
Guidelines for the clinical management of Lynch syndrome (hereditary non-polyposis cancer)
Correction: Functional analysis of BRCA1 M1628V variant
Genetics of dyslexia: the evolving landscape
Mosaicism in neurofibromatosis type 2: an update of risk based on uni/bilaterality of vestibular schwannoma at presentation and sensitive mutation analysis including multiple ligation-dependent probe
Cancer risks in carriers of the BRCA1/2 Ashkenazi founder mutations Ashkenazi
Gain-of-function gene mutations and venous thromboembolism: distinct roles in different clinical settings
Chromosome 11 segmental paternal isodisomy in amniocytes from two fetuses with omphalocoele: new highlights on phenotype-genotype correlations in Beckwith-Wiedemann syndrome
Measurement of the clinical utility of a combined mutation detection protocol in carriers of Duchenne and Becker muscular dystrophy
Abnormal sterol metabolism in holoprosencephaly: studies in cultured lymphoblasts
Familial 4.3 Mb duplication of 21q22 sheds new light on the Down syndrome critical region
Genetic enhancement of cognition in a kindred with cone-rod dystrophy due to RIMS1 mutation
Integrin  3 Leu33Pro polymorphism increases BRCA1-associated ovarian cancer risk
A hexanucleotide repeat upstream of eotaxin gene promoter is associated with asthma, serum total IgE and plasma eotaxin levels
Osteopoikilosis, short stature and mental retardation as key features of a new microdeletion syndrome on 12q14
Environmental influence on the worldwide prevalence of a 776C->G variant in the transcobalamin gene (TCN2)
The human GIMAP5 gene has a common polyadenylation polymorphism increasing risk to systemic lupus erythematosus
Genetic heterogeneity in Rubinstein-Taybi syndrome: delineation of the phenotype of the first patients carrying mutations in EP300
Borate transporter SLC4A11 mutations cause both Harboyan syndrome and non-syndromic corneal endothelial dystrophy
Phenotypic and population differences in the association between CILP and lumbar disc disease
Genotypes and phenotypes in children with short stature: clinical indicators of SHOX haploinsufficiency
Molecular characterisation of a mosaicism with a complex chromosome rearrangement: evidence for coincident chromosome healing by telomere capture and neo-telomere formation
X-linked retinoschisis: an update
Congenital disorder of glycosylation type Ia presenting with hydrops fetalis
Exon deletions of SPG4 are a frequent cause of hereditary spastic paraplegia
Sensorineural deafness and male infertility: a contiguous gene deletion syndrome
A comprehensive strategy for the subtyping of patients with Fanconi anaemia: conclusions from the Spanish Fanconi Anemia Research Network
Clinical and molecular cytogenetic characterisation of a newly recognised microdeletion syndrome involving 2p15-16.1