American Journal of Medical Genetics Part A - 2023

423 articles | Last updated: 2025-12-03 14:12:55
Caucasian
0
White
1
European
4
Other
26
Article Title Cauc. White Euro. Other Phrases Used
T A T A T A T A
High number of candidate gene variants are identified as disease‐causing in a period of 4 years
Radiological characteristics of skeletal growth in neonates and infants with achondroplasia Japanese
Late‐onset mucopolysaccharidosis type <scp>IIIA</scp> mimicking Usher syndrome
<scp>RASopathies</scp> are the most common set of monogenic syndromes identified by exome sequencing for nonimmune hydrops fetalis: A systematic review and meta‐analysis
Growth, body composition, and endocrine‐metabolic profiles of individuals with Kleefstra syndrome provide directions for clinical management and translational studies
A novel single‐base deletional mutation of <scp><i>MIP</i></scp> impairs protein distribution and cell‐to‐cell adhesion in autosomal dominant cataracts in a Chinese family
<i>TREX‐1</i> related Aicardi‐Goutières syndrome improved by Janus kinase inhibitor
Biallelic <i>LZTR1</i> variants in a 49‐year‐old woman with hypertrophic cardiomyopathy: A clue for considering <i>LZTR1</i> in adults
Double somatic mosaicism in <scp>Cornelia de Lange</scp> syndrome
A case of <scp><i>MBTPS1</i></scp>‐related disorder due to compound heterozygous variants in <scp><i>MBTPS1</i></scp> gene: Genotype–phenotype expansion and the emergence of a novel syndrome
A novel <scp><i>TTC26</i></scp> variant in a patient with hexadactyly, pituitary stalk interruption, hepatopathy, nephropathy, and bilateral lip‐palate cleft: A case report and expansion of the phenot
Long‐read genome sequencing reveals a novel intronic retroelement insertion in <scp><i>NR5A1</i></scp> associated with 46,<scp>XY</scp> differences of sexual development
Long‐term use of everolimus for refractory arrhythmia in a child with tuberous sclerosis complex
Expanding the phenotypic and genotypic spectrum of <scp>GGPS1</scp> related congenital muscular dystrophy
Multi‐locus pathogenic variation identified in a patient with craniosynostosis
Facial dysmorphology in children exposed in pregnancy to anticonvulsant medications correlates with deficits in <scp>IQ</scp>
Friends, Family, and Colleagues Remember Dr. John Opitz
Table of Contents, Volume 194A, Number 1, January 2024
In Memoriam: John M. Opitz, MD
In This Issue
A severe neurocognitive phenotype caused by biallelic <i>CHD3</i> variants in two siblings Iranian descent
Genetics of 21‐hydroxylase deficiency: Clinical presentation should guide the investigation
Exploring the evolving roles of clinical geneticists and genetic counselors in the era of genomic medicine
Letter to the Editor regarding “New cases of recently described <scp>Thauvin‐Robinet‐Faivre</scp> syndrome with a novel homozygous <scp><i>FIBP</i></scp> gene variant” by Kılıç and Koşukçu, “An invest
Recognizing the importance of adequate follow‐up for hearing impairment in trisomy 18
De novo variants identified by trio whole exome sequencing of bladder exstrophy epispadias complex
Patent ductus arteriosus and coarctation of the aorta in association with <scp><i>PRDM6</i></scp> variants
A patient with <scp>Pitt–Hopkins</scp> syndrome with concomitant common variable immunodeficiency
Genetic counselors' utilization of <scp>ChatGPT</scp> in professional practice: A <scp>cross‐sectional</scp> study
Development and validation of a computable phenotype for Turner syndrome utilizing electronic health records from a national pediatric network
Growing up with Marshall syndrome: A case report from infancy to age 12.5 years
Cause, severity, and efficacy of treatment for hearing loss in children with Trisomy 18: A single institution‐based retrospective study
Clinical course and therapeutic trial for a case of congenital secretory diarrhea due to novel <i>GUCY2C</i> variant
Maternal <scp><i>CHD7</i></scp> gonosomal mosaicism in a fetus with <scp>CHARGE</scp> syndrome
The functional study of a novel <scp>MKRN3</scp> missense mutation associated with familial central precocious puberty Chinese
<scp>RNA</scp> sequencing reveals deep intronic <scp><i>CEP120</i></scp> variant: A report of the diagnostic odyssey for two siblings with Joubert syndrome type 31
<scp><i>SAMHD1</i></scp> compound heterozygous rare variants associated with moyamoya and mitral valve disease in the absence of other features of <scp>Aicardi–Goutières</scp> syndrome
Refining the activities of genetic assistants: Development of task statements applicable across practice settings
An adult patient with <scp>Tatton–Brown–Rahman</scp> syndrome caused by a novel <scp><i>DNMT3A</i></scp> variant and axonal polyneuropathy
Time to diagnosis in rapid exome/genome sequencing in the clinical inpatient setting
Stratification of the risk of ovarian dysfunction by studying the complexity of intermediate and premutation alleles of the <scp><i>FMR1</i></scp> gene
John M Opitz: Physician, morphologist, scholar, editor (1935–2023)
Ophthalmic manifestations of Czech dysplasia
Two novel heterozygous exonic deletions lead to Chanarin–Dorfman syndrome in a patient with congenital ichthyosis, sensorineural hearing loss, and liver dysfunction Venezuelan descent
“We are not a typical family anymore”: Exploring the experiences and support needs of fathers of children with <scp>Fragile X</scp> syndrome in <scp>Australia</scp>
Cat eye syndrome: Clinical, cytogenetics and familial findings in a large cohort of 43 patients highlighting the importance of congenital heart disease and inherited cases
A novel variant in <i>CYFIP2</i> in a girl with severe disabilities and bilateral perisylvian polymicrogyria
The <scp>8th International RASopathies Symposium</scp>: Expanding research and care practice through global collaboration and advocacy
Ocular manifestations in a cohort of 43 patients with <scp>KBG</scp> syndrome
Biallelic variants of the first Kunitz domain of <scp>SPINT2</scp> cause a non‐syndromic form of congenital diarrhea and tufting enteropathy
Clinical phenotypes of individuals with <scp>Chung–Jansen</scp> syndrome across age groups
Isolated cardiomyopathy in a pathogenic X‐linked in frame hemizygous <scp>DMD</scp> exon 49 deletion: A rare presentation with normal creatine kinase levels and absence of musculoskeletal symptoms
Molecular characterization of 13 patients with <scp><i>PIK3CA</i></scp>‐related overgrowth spectrum using a targeted deep sequencing approach
Table of Contents, Volume 191A, Number 12, December 2023
In This Issue
Neolithic Community Revealed Using Ancient <scp>DNA</scp> Data
Publication schedule for 2023
Heteroplasmic pathogenic m.<scp>12315G</scp>&gt;A variant in <scp><i>MT‐TL2</i></scp> presenting with <scp>MELAS</scp> syndrome and depletion of nitric oxide donors
Sequencing the Y Chromosome
Unexpected findings in cervical spine in spondylometaphyseal dysplasia Sutcliff type <scp><i>FN1</i></scp>‐related
A novel <scp><i>KNL1</i></scp> intronic splicing variant likely destabilizes the <scp>KMN</scp> complex, causing primary microcephaly
Calloso‐adreno‐scrotal agenesis associated with biallelic <scp>MAPK</scp>‐activating death domain protein (<scp>MADD</scp>) variant: Further phenotypic delineation of <scp>MADD</scp> deficiency
Undifferentiated psychosis or schizophrenia associated with vermis‐predominant cerebellar hypoplasia
Vertebral artery dissection caused by atlantoaxial dislocation in a patient with Marfan syndrome
Application of the <scp>Face2Gene</scp> tool in an Italian dysmorphological pediatric clinic: Retrospective validation and future perspectives
Genome sequencing detects a balanced pericentric inversion with breakpoints that impact the <scp><i>DMD</i></scp> and upstream region of <scp><i>POU3F4</i></scp> genes
A novel homozygous variant in <scp><i>ATL1</i></scp> associated with early onset spastic paraplegia <scp>3A</scp>: Further evidence for autosomal recessive inheritance "consanguineous Arabic families" and "a consanguineous Arabic family"
Phenotypic heterogeneity associated with <scp><i>KIF21A</i></scp>: Two new cases and review of the literature
Understanding recessive disease risk in multi‐ethnic populations with different degrees of consanguinity
Aortic dissection in a young male with persistent ductus arteriosus and a novel variant in <scp><i>MYLK</i></scp>
Hearing loss and history of otolaryngological conditions in adults with microdeletion 22q11.2
Genotype and phenotype characterization of primary hypertrophic osteoarthropathy type 2 and chronic enteropathy associated with <scp><i>SLCO2A1</i></scp>: Report of two cases and literature review Asian origin
Arterial tortuosity in pediatric Loeys‐Dietz syndrome patients
First report on female monozygotic twins discordant for congenital nephrogenic diabetes insipidus
Probable digenic inheritance of <scp>Diamond–Blackfan</scp> anemia
45,X/46,<scp>XY</scp> mosaicism: Clinical manifestations and long term <scp>follow‐up</scp>
Phenotypic and genotypic characterization of 1q21.1 copy number variants: A report of 34 new individuals and literature review
Indian patients with <scp>CHST3</scp>‐related chondrodysplasia with congenital joint dislocations
New cases of recently described <scp>Thauvin‐Robinet‐Faivre</scp> syndrome with a novel homozygous <i>FIBP</i> gene variant
Neurodevelopmental and other phenotypes recurrently associated with heterozygous <scp><i>BAZ2B</i></scp> loss‐of‐function variants
Clinical relevance of genetic variants in the von Willebrand factor according to in‐silico methods
Novel compound heterozygous <scp><i>ATP1A2</i></scp> variants in a patient with fetal akinesia/hypokinesia sequence
The importance of patient‐specific resources for families dealing with prenatal rare diseases
The phenotypic heterogeneity of the variant m.5537_5538insT in <i>MT‐TW</i> does not only depend on the heteroplasmy rates
A case of mosaic deletion of paternally‐inherited <scp><i>PLAGL1</i></scp> and two cases of upd(6)mat add to evidence for <scp><i>PLAGL1</i></scp> under‐expression as a cause of growth restriction
Homozygous deletion of the <i>DSG3</i> terminal exon associated with acantholytic blistering of the oral and laryngeal mucosa
Characterization of seizures and <scp>EEG</scp> findings in creatine transporter deficiency due to <scp>SLC6A8</scp> mutation
A mesomelic skeletal dysplasia, Kantaputra‐like, not related to <i>HOXD</i> cluster region, and with phenotypic gender differences Brazilian family
Publication schedule for 2023
Table of Contents, Volume 191A, Number 11, November 2023
Topical Gene Therapy Restores Vision in Ocular Dystrophic Epidermolysis Bullosa
The Willingness to Participate in Genetic Studies may be Genetic
In This Issue
<scp><i>EED</i></scp> related overgrowth: First report of multiple members in a single family
A novel de novo intragenic duplication in <scp><i>FBN1</i></scp> associated with early‐onset Marfan syndrome in a 16‐month‐old: A case report and review of the literature
Epilepsy in cardiofaciocutaneous syndrome: Clinical burden and response to anti‐seizure medication
Inspiring New Science to Guide Healthcare in Turner Syndrome: Rationale, design, and methods for the InsighTS Registry
Growth reference charts for children with hypochondroplasia
Substantial incidence of bladder dysfunction in patients with <scp>VACTERL</scp> association: Implications for surveillance
Causes of death in individuals with trisomy 18 after the first year of life
Psychiatrists' perceptions of and reactions to a simulated psychiatric genetic counseling session
Craniosynostosis in molecularly diagnosed <scp>Kabuki</scp> syndrome: Prevalence and clinical implications
<scp>Vissers‐Bodmer</scp> syndrome caused by a novel de novo <scp><i>CNOT1</i></scp> frameshift variant
<scp>Live‐born</scp> autosomal ring chromosomes at the Johns Hopkins Hospital Cytogenomics Laboratory: Case series—Spanning 52 years of experience in a single center
Adapting a quality of life scale for children and young people with <scp>Down</scp> syndrome in <scp>Chile</scp>
Refining the phenotypic spectrum of <i>CCDC88A</i>‐related <scp>PEHO</scp>‐like syndrome
The <i>IFITM5</i> Ser40Leu variant can manifest as prenatal Caffey disease
Annular pancreas in two sisters: The story goes on
Growth in puberty in girls with hypochondroplasia, p.Asn540Lys‐related mutations
Clinical utility of early rapid genome sequencing in the evaluation of patients with differences of sex development
<scp>ACBD5</scp>‐related retinal dystrophy with leukodystrophy due to novel mutations in <i>ACBD5</i> and with additional features including ovarian insufficiency
<scp>Tatton‐Brown–Rahman</scp> syndrome: Novel pathogenic variants and new neuroimaging findings
Pathogenic variant in the X‐linked <i>ARR3</i> gene associated with variable early‐onset myopia
Diagnostic yield of chromosomal microarray in the largest Latino clinical cohort
Bone health in <i>SATB2</i>‐associated syndrome: Results from a large prospective cohort and recommendations for surveillance
Parental age effects and Rett syndrome
Influences of sex chromosome aneuploidy on height, weight, and body mass index in human childhood and adolescence
Looking back and beyond the 2017 diagnostic criteria for hypermobile <scp>Ehlers‐Danlos</scp> syndrome: A retrospective cross‐sectional study from an Italian reference center
Prenatal and infantile diagnosis of craniosynostosis in individuals with RASopathies
Long term outcomes in children with trichohepatoenteric syndrome
Growth charts in <scp>DYRK1A</scp> syndrome
Expanding the phenotype of Brunner syndrome from childhood to adulthood: Description of the second pediatric patient and his mother
A recurrent <scp><i>KCNK4</i></scp> variant in a dominant pedigree with hypertrichosis and gingival fibromatosis syndrome: <scp>Variable</scp> phenotypic expressivity and insights on patients' dental
Early development and adaptive functioning in children with Bardet‐Biedl syndrome
A familial deletion of 10p12.1 associated with thrombocytopenia
Moebius syndrome and gastroschisis—The second case of a rare association
A qualitative evaluation of patient and parent experiences with an undiagnosed diseases program
Pseudo‐eye‐of‐the‐tiger sign in cerebellar ataxia with neuropathy and vestibular areflexia syndrome (<scp>CANVAS</scp>)
De novo missense variants in <i>ZBTB47</i> are associated with developmental delays, hypotonia, seizures, gait abnormalities, and variable movement abnormalities
ACMG Seeks to Advance Equitable Access to Clinical Genetics/Genomics Testing
New Framework Released on Using Population Descriptors in Genetics and Genomics Research
Rule out compound heterozygous exonic/deep intronic <i>ABCA4</i> variants in an MNGIE patient with Stargardt disease
Response to “Letter to the editor” regarding “Rule out compound heterozygous exonic/deep intronic <i>ABCA4</i> variants in an MNGIE patient with Stargardt disease”
In This Issue
Table of Contents, Volume 191A, Number 10, October 2023
Publication schedule for 2023
Dominant frontonasal dysplasia with ectodermal defects results from increased activity of <i>ALX4</i>
Saliva <scp>DNA</scp>: An alternative biospecimen for single nucleotide polymorphism chromosomal microarray analysis in autism
Woodhouse–Sakati syndrome in an Indian patient with a novel pathogenic variant Indian; southern India; Greater Middle Eastern countries
Microcystic lymphatic malformations in Turner syndrome are due to somatic mosaicism of <scp><i>PIK3CA</i></scp>
An atypical <scp>Aymé‐Gripp</scp> phenotype detected by exome sequencing
Identification of the first homozygous intragenic deletion in the <scp>YY1AP1</scp> gene in a consanguineous family: New insights into the phenotypic variability associated with Grange syndrome
Variable phenotype of a null <i>PPP1R13L</i> allele in children with dilated cardiomyopathy
Effectiveness of cardiac palliative surgery for trisomy 18 patients with increased pulmonary blood flow
Systematic ophthalmologic evaluation in cardio‐facio‐cutaneous syndrome: A genotype–endophenotype correlation
Musculoskeletal phenotypes in 3q29 deletion syndrome
Monozygotic twins discordant for a congenital cranial dysinnervation disorder with features of Moebius syndrome
Heterozygous gain of function variants in a critical region of <scp><i>RNF13</i></scp> cause congenital microcephaly, epileptic encephalopathy, blindness, and failure to thrive
Impact of tracheostomies on the long‐term survival of patients with trisomy 13 syndrome
Expansion of the phenotypic spectrum associated with pathogenic missense variation in <scp><i>DHX16</i></scp>
Are <scp><i>CUL3</i></scp> variants an underreported cause of congenital heart disease?
The mitochondrial tRNA MT‐TW m.5537_5538insT variant presents with significant intra‐familial clinical variability
Atlantoaxial instability associated with <i>ALDH18A1</i> mutation
Ear anomalies and hearing loss in patients with <scp>VACTERL</scp> association and the effect of maternal diabetes Hispanic ancestry
A Japanese patient with <scp>Teebi</scp> hypertelorism syndrome and a novel <scp><i>CDH11</i> EC1</scp> domain variant
Genetic syndromes are prevalent in patients with comorbid neurodevelopmental disorders and catatonia
Beckwith–Wiedemann syndrome with multiple hepatic and cutaneous hemangiomas in a female patient of Albanian origin: Diagnostic and therapeutic considerations Albanian origin
A novel report of a fertile female with partial <scp>Y</scp> chromosome gain completing a healthy pregnancy
Further characterization of <scp><i>CEP85L</i></scp>‐associated lissencephaly type 10: Report of a three‐generation family and review of the literature
A medical odyssey of a 72‐year‐old man with Charcot–Marie–Tooth disease type 2 newly diagnosed with biallelic variants in <i>SORD</i> gene causing sorbitol dehydrogenase deficiency
Partial penetrance and phenotypic variability of aplasia of lacrimal and salivary glands caused by a novel <scp><i>FGF10</i></scp> donor splice‐site mutation
Clinical and genetic characterization of a Chinese family with pontocerebellar hypoplasia type 7
A homozygous missense variant in the <scp><i>PLCB4</i></scp> gene causes severe phenotype of auriculocondylar syndrome type 2
Polygenic Scores Fall Short on Diversity
Publication schedule for 2023
Table of Contents, Volume 191A, Number 9, September 2023
Health Insurance Denials Limit Access to Genetic Testing
In This Issue
Novel association of Dandy–Walker malformation with <scp><i>CAPN15</i></scp> variants expands the phenotype of oculogastrointestinal neurodevelopmental syndrome
Thiamine metabolism dysfunction syndrome 5 (<scp>THMD5</scp>) mimicking acute disseminated encephalomyelitis
Congenital diaphragmatic hernia in siblings with <scp><i>PIGA</i></scp>‐related congenital disorder of glycosylation
A novel pathogenic variant c.<scp>262delA</scp> in <scp><i>PBX1</i></scp> causing oligomeganephronia identified using whole‐exome sequencing and a literature review
Epidemiology of spinal muscular atrophy caused by <scp><i>SMN1</i></scp> deletions in Maritime Canada
An incidental finding in prenatal exome sequencing—A case study and review of the clinical and ethical considerations
Α rare case of myopathy, lactic acidosis, and severe rhabdomyolysis, due to a homozygous mutation of the ferredoxin‐2 (<scp><i>FDX2</i></scp>) gene
A Noonan‐like pediatric patient with a de novo <i>CBL</i> pathogenic variant and an <i>RNF213</i> polymorphism p.R4810K presenting with cardiopulmonary arrest due to left main coronary artery ostial a
The smallest likely pathogenic duplication of a <scp><i>SOX9</i></scp> enhancer identified to date in a family with 46,<scp>XX</scp> testicular differences of sex development
Case of <i>CLPB</i> deficiency solved by HiFi long read genome sequencing and RNAseq
Subdural hemorrhage, macrocephaly, rash, and developmental delay in an infant: A pathogenic variant in <scp><i>NLRP3</i></scp> causes <scp>CINCA</scp>/<scp>NOMID</scp>
A 22q13.1 duplication in mosaicism including <i>SOX10</i>
Ocular manifestations of mitochondrial neurogastrointestinal encephalomyopathy: A case report and literature review
Pathogenicity analysis and splicing rescue of a classical splice site variant (c.1343+<scp>1G</scp>&gt;<scp>T</scp>) of <scp><i>CNOT1</i></scp> gene associated with neurodevelopmental disorders
An evaluation of clinical presentation and genetic testing approaches for patients with neuromuscular disorders
Characteristics of hearing impairment in patients with trisomy 18
Neurofibromatosis‐ and schwannomatosis‐associated tumors: Approaches to genetic testing and counseling considerations
Compound heterozygous variants in <scp><i>MAPK8IP3</i></scp> were detected in severe congenital hypotonia mimicking lethal spinal muscular atrophy
In Memoriam: Charles R. Scriver (1930–2023)
In This Issue
Table of Contents, Volume 191A, Number 8, August 2023
Publication schedule for 2023
American College of Medical Genetics Issues Guidance on Polygenic Risk Scores
Cover Image, Volume 191A, Number 8, August 2023
A case of <i>LSS</i>‐associated congenital nuclear cataract with hypotrichosis and literature review
The importance of age‐specific gene expression
Associated anomalies in <scp>Pierre Robin</scp> sequence
Novel homozygous <scp><i>LAMB1</i></scp> in‐frame deletion in a pediatric patient with brain anomalies and cerebrovascular event
Revisiting the diagnosis of Gaucher disease in a family with multiple <scp><i>GBA1</i></scp> variants
<i>ZFHX4</i> truncating variant and orofacial clefting
Clinical and molecular heterogeneity of syndromic hypothalamic hamartoma
15q26.3 deletions distal to <scp><i>IGF1R</i></scp> cause growth retardation, congenital heart defect and skeletal anomalies: Case report and review of literature
Turner syndrome may be associated with hepatic adenoma
Early initiation of <scp>B</scp>‐vitamin supplementation may reduce symptoms and explain intrafamilial variability: Insights from two sibling pairs from the <scp>TANGO2</scp> natural history study
Isolated frontosphenoidal craniosynostosis: An argument for genetic testing
The social phenotype associated with <scp>Wiedemann‐Steiner</scp> syndrome: Autistic traits juxtaposed with high social drive and prosociality
Clinical, biochemical, and molecular characterization of mucopolysaccharidosis type <scp>III</scp> in 34 <scp>Egyptian</scp> patients
Confirmation of gray matter heterotopia as part of the <scp><i>DDX23</i></scp> phenotypic spectrum
Correction to “A mutational hotspot in <i>AMOTL1</i> defines a new syndrome of orofacial clefting, cardiac anomalies, and tall stature”
The importance of gynecological examination in adolescent girls and adult women with <scp>Prader–Willi</scp> syndrome
Updated consensus guidelines on the management of Phelan–McDermid syndrome
A recurrent homozygous <scp><i>LMNA</i></scp> missense variant p.<scp>Thr528Met</scp> causes atypical progeroid syndrome characterized by mandibuloacral dysostosis, severe muscular dystrophy, and skel
A nonsense variant in the N‐terminal acetyltransferase <i>NAA30</i> may be associated with global developmental delay and tracheal cleft
Genomic analyses in Cornelia de Lange Syndrome and related diagnoses: Novel candidate genes, <scp>genotype–phenotype</scp> correlations and common mechanisms
Clinical and molecular characterization in a cohort of patients with progressive pseudorheumatoid dysplasia Egyptian
Homozygous 22q11.2 distal type <scp>II</scp> microdeletion is associated with syndromic neurodevelopmental delay
The spectrum of hereditary neuromuscular disorders in the Pakistani population patients of European descent; Pakistani population; populations that have possible shared ancestry with the Pakistani population
Correction to “The spectrum of neurological manifestations and genotype–phenotype correlation in Indian children with Gaucher disease”
Heterozygous variants in <scp><i>TBCK</i></scp> cause a mild neurologic syndrome in humans and mice
Five siblings expand the spectrum of <i>GPC6</i>‐related skeletal dysplasia
Homozygous splice site variant affecting the first von <scp>Willebrand</scp> factor <scp>A</scp> domain of <scp><i>COL12A1</i></scp> in a patient with myopathic <scp>Ehlers‐Danlos</scp> syndrome
Proximal 1q21 duplication: A syndrome or a susceptibility locus?
Rare variants found in multiplex families with orofacial clefts: Does expanding the phenotype make a difference?
Clinical and radiological assessment of scoliosis in Koolen‐de Vries syndrome
An exploratory study of plasma ceramides in comorbidities in Down syndrome
Missense variant in <i>SRCAP</i> with distinct DNA methylation signature associated with non‐FLHS SRCAP‐related neurodevelopmental disorder
Healthcare experiences of patients with Down syndrome from primarily Spanish‐speaking households
A novel biallelic frameshift variant in <i>C2orf69</i> causing developmental regression, seizures, microcephaly, autistic features, and hypertonia
Further validation of craniosynostosis as a part of phenotypic spectrum of <scp><i>BCL11B</i></scp>‐related <scp>BAFopathy</scp>
Ambiguous genitalia, giant congenital melanocytic nevus and subpulmonic outlet ventricular septal defect in an African child with Neurofibromatosis 1 African; sub-Saharan Africa
Exploring collaboration models between geneticists and intensivists for implementing rapid genome sequencing in critical care settings
A qualitative exploration of patient perspectives on psychosocial burdens and positive factors in adults with osteogenesis imperfecta
Identification and molecular characterization of two recurrent missense mutations in the <scp><i>RS1</i></scp> gene in two families with X‐linked retinoschisis from North India
Incidence and outcome of arrhythmias and electrical disease in patients with Trisomy 18
<i>PUF60</i>‐related developmental disorder: A case series and phenotypic analysis of 10 additional patients with monoallelic <i>PUF60</i> variants
Expanding the phenotype of anauxetic dysplasia caused by biallelic <scp><i>NEPRO</i></scp> mutations: A case report
Exome sequencing in a Romanian <scp>Bardet‐Biedl</scp> syndrome cohort revealed an overabundance of causal <scp><i>BBS12</i></scp> variants Europe; Eastern European; Romani origin
Oculoauriculofrontonasal syndrome: Refining the phenotype through a new case series and literature review
Bubonic Plague Protector Shows Its Dark Side
Genomic Analysis Unlocks Cause Of Beethoven's Death
Table of Contents, Volume 191A, Number 7, July 2023
Publication schedule for 2023
In This Issue
Aneurysms involving the coronary arteries in a neonate with neurofibromatosis 1
Biallelic variants in <scp><i>NUDCD2</i></scp> associated with a multiple malformation syndrome with cholestasis and renal failure
Views on the impact of the <scp>COVID</scp>‐19 pandemic on health in people with Down syndrome from diverse backgrounds
Pediatric pulmonary arterial hypertension due to a novel homozygous <scp><i>GDF2</i></scp> missense variant affecting <scp>BMP9</scp> processing and activity
An in‐frame deletion affecting the critical acid loop of <scp><i>PPP2R5D</i></scp> is associated with a neonatal lethal form of <scp><i>PPP2R5D</i></scp>‐related neurodevelopmental disorder
The contribution of mosaicism to genetic diseases and de novo pathogenic variants
<i>TOPORS</i> as a novel causal gene for Joubert syndrome Dominican descent; Dominican ancestry
Documentation and prevalence of prenatal and neonatal outcomes in a cohort of individuals with <scp>KBG</scp> syndrome non-Hispanic and Hispanic populations
<scp>ConsCal</scp>: A tool to aid medical genetics professionals in consanguineous populations
Maternally inherited deletion encompassing the <scp><i>RTL1as</i></scp> and <scp><i>MEG8</i></scp> genes of the human 14q32 imprinted region in a patient with a mild Kagami‐Ogata syndrome phenotype
Correspondence: Perspectives on the future of dysmorphology
Expanding the phenotype and genotype in Thauvin‐Robinet‐Faivre syndrome: A new patient with a novel variant and additional clinical findings
Multifocal heterotopic ossification in a man with germline variants of <scp>LIM</scp> Mineralization Protein‐1 (<scp>LMP</scp>‐1)
Retrospective identification of patients with <i>SRRM2</i>‐related neurodevelopmental disorder in a single tertiary children's hospital
Recessive <scp><i>CHRM5</i></scp> variant as a potential cause of neurogenic bladder
Generation of tandem alternative splice acceptor sites and <scp><i>CLTC</i></scp> haploinsufficiency: A cause of <scp><i>CLTC</i></scp>‐related disorder
Expanding the genetic spectrum of <scp>ALKU</scp> syndrome: Compound heterozygosity for two deleterious variants in <scp><i>SMG8</i></scp> gene European population
A very mild phenotype in six individuals of a three‐generation family with the novel <scp><i>HRAS</i></scp> variant c.<scp>176C</scp> &gt; <scp>G</scp> p.(<scp>Ala59Gly</scp>): Emergence of a new <scp
Anemia and thrombocytopenia due to a novel <scp><i>BRPF1</i></scp> variant in a family from Çanakkale with intellectual disability and dysmorphic facies: Case report and review of the literature
<scp>Jansen‐de Vries</scp> syndrome: Expansion of the <scp><i>PPM1D</i></scp> clinical and phenotypic spectrum in 34 families
<scp><i>CHST3</i></scp>‐related skeletal dysplasia in 14 patients: Identification of 8 novel variants and further expansion of the phenotypic spectrum
Global health measures from a <scp>N</scp>ational <scp>D</scp>own <scp>S</scp>yndrome <scp>R</scp>egistry
<scp>PHACES</scp>‐like syndrome with <scp><i>TMEM260</i></scp> compound heterozygous variants
Expansion of clinical and variant spectrum of <i>EEF2</i>‐related neurodevelopmental disorder: Report of two additional cases
Report of new variants in <scp><i>PPIL1</i></scp> underlying type 14 pontocerebellar hypoplasia and their associated phenotypic manifestations in two fetuses
Persistent chylothorax associated with lymphatic malformation type 6 due to biallelic pathogenic variants in <scp><i>PIEZO1</i></scp>
Publication schedule for 2023
Table of Contents, Volume 191A, Number 6, June 2023
Fertility Clinic Sued for Implanting Embryo Carrying Cancer Gene
In This Issue
<scp><i>SOX2</i></scp> pathogenic variants with normal eyes: Expanding the phenotypic spectrum
Cover Image, Volume 191A, Number 6, June 2023
Promising Results with Direct‐to‐Brain Gene Therapy
A homozygous <scp>Gly470Ala</scp> variant in <scp><i>PEX6</i></scp> causes severe <scp>Zellweger</scp> spectrum disorder Mixtec ancestry; Mixtec population of Central California
Multiple facial angiofibromas: A manifestation of Frank‐ter Haar syndrome?
Do <scp><i>PACS1</i></scp> variants impeding adaptor protein binding predispose to syndromic intellectual disability?
Craniofacial and dental characteristics of three Japanese individuals with genetically diagnosed <scp><i>SATB2</i></scp>‐associated syndrome
Triplications of chromosome 1p36.3, including the genes <i>GABRD</i> and <i>SKI</i>, are associated with a developmental disorder and a facial gestalt
Clinical and radiological heterogeneity for the rare <scp>FGFR3</scp> variant, p.<scp>Ser344Cys</scp>, description of a third patient
Portal cavernoma in type 1 neurofibromatosis: A fortuitous or causal association?
Inpatient epidemiology, healthcare utilization, and association with comorbidities of Turner syndrome: A National Inpatient Sample study
Uniparental disomy of multiple chromosomes in two cases with a complex phenotype
A de novo <scp><i>U2AF2</i></scp> heterozygous variant associated with hypomyelinating leukodystrophy
De novo <scp><i>RANBP2</i></scp> variant in a fetal demise case with cerebral intraparenchymal hemorrhage
Generation and mutational analysis of a transgenic murine model of the human <i>MAF</i> mutation
Somatic symptoms, pain, catastrophizing and the association with disability among children with heritable connective tissue disorders
<scp><i>U2AF2</i></scp> variant in a patient with developmental delay, dysmorphic features, and epilepsy
Autosomal dominant inheritance with sex‐limited manifestation: The jury is still out
Parallel deletion and duplication at 7q11.23 in a silent carrier for two reciprocal syndromic disorders
Correction to “Expanding the phenotype: Four new cases and hope for treatment in <scp>Bachmann–Bupp</scp> syndrome”
Long‐term effectiveness of enzyme replacement therapy in Fabry disease with the p.Arg227Ter variant: Fabry disease in Ostrobothnia (FAST) study
Cognitive, adaptive and behavioral profile in Sotos syndrome children with 5q35 microdeletion or intragenic variants
A <i>PUS7</i> gene pathogenic variant causing self‐injurious behavior, sleep disturbances, and developmental delay: A case report
Novel mosaic <scp><i>TRAF7</i></scp> likely pathogenic variant in an African American family African American; African American ancestry
Novel nonsense mutation in <i>UNC80</i> in a <scp>T</scp>urkish patient further validates the sociable skill and severe gastrointestinal problems as part of disease spectrum Turkish
Expanded phenotypic and hematologic abnormalities beyond bone marrow failure in <i>MECOM</i>‐associated syndromes
The clinical phenotype of Koolen‐de Vries syndrome in Turkish patients and literature review Turkish
First experience of combined enzyme replacement therapy and hematopoietic stem cell transplantation in <scp>alpha‐mannosidosis</scp>
Development of informant‐report neurobehavioral survey scales for <scp>PTEN</scp> hamartoma tumor syndrome and related neurodevelopmental genetic syndromes
Novel <scp><i>NALCN</i></scp> variant linked to temporal lobe epilepsy
The <scp>D409H</scp> variant in <scp><i>GBA1</i></scp>: Challenges in predicting the Gaucher phenotype in the newborn screening era
Biallelic variants in <scp><i>TUBGCP6</i></scp> result in microcephaly and chorioretinopathy 1: Report of four cases and a literature review
Novel insights on <i>GTPBP3</i>‐associated hypertrophic cardiomyopathy
The Society for Craniofacial Genetics and Developmental Biology 45th Annual Meeting
In This Issue
Publication schedule for 2023
Table of Contents, Volume 191A, Number 5, May 2023
American Society of Human Genetics Releases Apology for Misuse of Genetic Research
Pontocerebellar hypoplasia associated with p.<scp>Arg183Trp</scp> homozygous variant in <scp><i>EXOSC1</i></scp> gene: A case report
Metabolomics as a Diagnostic Tool
Quantitative measures of motor development in Angelman syndrome
Adverse childhood experiences and the development of <scp>Down</scp> syndrome regression disorder
Expanding the phenotype of Seckel syndrome associated with biallelic loss‐of‐function variants in <scp><i>CEP63</i></scp>
Long‐term follow‐up of a patient with neonatal form of Gaucher disease
The range of publications on arthrogryposis multiplex congenita from 1995 to 2022—A scoping review
Extending the phenotypes associated with <scp><i>TRIO</i></scp> gene variants in a cohort of 25 patients and review of the literature
<scp><i>H4C5</i></scp> missense variant leads to a neurodevelopmental phenotype overlapping with Angelman syndrome
<scp>RNA</scp> sequencing to support intronic variant interpretation: A case report of <scp><i>TRAPPC12</i></scp>‐related disorder
Cardiometabolic risk in young adults with <scp>Down</scp> syndrome
A novel <scp><i>RYR1</i></scp> variant in an infant with a unique fetal presentation of central core disease
Clinical exome sequencing findings in 1589 patients
A study of disparities in access to genetic care pre‐ and post‐pandemic
ABL1‐related congenital heart defects and skeletal malformations syndrome in a patient from Sub‐Saharan Africa: A case report highlighting novel cardiac features Sub‐Saharan Africa
Clinical insights from an unusual Turner syndrome manifestation: Congenital cutis verticis gyrata
De novo triplication at 1p36.23p36.22 further refines the dosage sensitive region of overlap in Setleis syndrome (focal facial dermal dysplasia type <scp>III</scp>)
Exome‐wide assessment of isolated biliary atresia: A report from the <scp>National Birth Defects Prevention Study</scp> using child–parent trios and a case–control design to identify novel rare varian
Chromosome 6p25 deletion syndrome: A case report and review of ophthalmic features
Long‐term outcomes in <scp>ALG13‐Congenital Disorder of Glycosylation</scp>
High‐depth next‐generation sequencing panel testing in the evaluation of arteriovenous malformations
An investigation of the etiology and follow‐up findings in 35 children with overgrowth syndromes, including biallelic <i>SUZ12</i> variant
Prevalence and descriptive epidemiology of Turner syndrome in the United States, 2000–2017: A report from the National Birth Defects Prevention Network
Breakpoint analysis for cytogenetically balanced translocation revealed unexpected complex structural abnormalities and suggested the position effect for <scp><i>MEF2C</i></scp>
Developmental disorder and spastic paraparesis in two sisters with a <scp><i>TCF7L2</i></scp> truncating variant inherited from a mosaic mother
<scp><i>PAK1</i></scp> c.<scp>1409 T</scp> &gt; a (p. <scp>Leu470Gln</scp>) de novo variant affects the protein kinase domain, leading to epilepsy, macrocephaly, spastic quadriplegia, and hydrocephalu
Publication schedule for 2023
In Loving Memory of Mary Kaye Richter (1945–2022)
In This Issue
Table of Contents, Volume 191A, Number 4, April 2023
The Human Genome Sequence is now Complete
A cryptic pathogenic <scp><i>NDUFV1</i></scp> variant identified by <scp>RNA</scp>‐seq in a patient with normal complex I activity in muscle and transient magnetic resonance imaging changes
<scp><i>MT‐ATP6</i></scp> mitochondrial disease identified by newborn screening reveals a distinct biochemical phenotype
Insights into the genotype–phenotype relationship of ocular manifestations in Kabuki syndrome
Autosomal dominant inheritance with sex‐limited infertility
An atypically mild case of ethylmalonic encephalopathy with pathogenic <scp><i>ETHE1</i></scp> variant
Venous malformation may be a feature of EXT1‐related hereditary multiple exostoses: A report of two unrelated probands
Predicting factors of neurodevelopmental performance in children with phenylketonuria Portuguese cohort
<scp><i>NOTCH1</i></scp> loss of the <scp>TAD</scp> and <scp>PEST</scp> domain: An antimorph?
Before diagnosing a stroke‐like episode, a stroke‐like lesion must be documented on multimodal cerebral <scp>MRI</scp>
Novel filamin C (<i>FLNC</i>) variant causes a severe form of familial mixed <scp>hypertrophic‐restrictive</scp> cardiomyopathy French‐Canadian descent
Whither social media and clinical genetics?
Neonatal lupus is a novel cause of positive newborn screening for X‐linked adrenoleukodystrophy
Prevalence of cardiovascular manifestations in patients with hypermobile <scp>Ehlers‐Danlos</scp> syndrome at the University of Miami
<scp><i>SOX5</i></scp>: <scp>Lamb–Shaffer</scp> syndrome—A case series further expanding the phenotypic spectrum
Chung–<scp>Jansen</scp> syndrome can mimic <scp>Cornelia de Lange</scp> syndrome: Another player among chromatinopathies?
A novel <i>de novo</i> pathogenic variant in <scp><i>TBL1XR1</i></scp> as a new proposed cause of Pierpont syndrome
Diagnosis of <scp><i>TBC1D32</i></scp>‐associated conditions: Expanding the phenotypic spectrum of a complex ciliopathy
Behold the appearance of the seemingly “<i>absent</i>” fibula: Reconsidering the taxonomy of congenital limb anomalies
Novel blended <scp><i>SNRPE</i></scp>‐related spliceosomopathy phenotype characterized by microcephaly and congenital atrichia
Severe congenital neutropenia, <i>SRP54</i> pathogenicity, and a framework for surveillance
Bisphosphonate treatment at s<scp>pondylo‐ocular</scp> syndrome due to a novel compound heterozygote variant in <scp><i>XYLT2</i></scp> and review of the literature
A likely pathogenic <scp><i>ACTG1</i></scp> variant in a child showing partial phenotypic overlap with Baraitser‐Winter syndrome
Phenotypic variability and gastrointestinal manifestations/interventions for growth in <scp><i>NAA10</i></scp>‐related neurodevelopmental syndrome
Correction to “Vestibular and audiological findings in the Alport <scp>syndrome</scp>”
Severe early‐onset overgrowth in a case of pseudohypoparathyroidism type 1b, caused by <i>STX16</i> deletion
Co‐occurrence of Proteus syndrome and ventricular tachycardia cardiac arrest in a teenager
History and highlights of the teratological collection in the<i>Narrenturm</i>, Vienna (Austria)
Expanding the reproductive organ phenotype of <i>CHD7</i>‐spectrum disorder
<i>TELO2</i>‐related syndrome (<scp>You‐Hoover‐Fong</scp> syndrome): Description of 14 new affected individuals and review of the literature
Portrait of autosomal recessive diseases in the <scp>French‐Canadian</scp> founder population of <scp>Saguenay‐Lac‐Saint‐Jean</scp> French-Canadian; Saguenay-Lac-Saint-Jean (founder population)
Rock around <i>DYRK1A</i>: Ethnic diversity, clinical challenges "ethnic diversity" (title); "different ethnicity"; "ethnic influences in the facial appearance" (abs
Publication schedule for 2023
Cover Image, Volume 191A, Number 3, March 2023
Pompe's Disease Successfully Treated In Utero
Nosology of genetic skeletal disorders: 2023 revision
Table of Contents, Volume 191A, Number 3, March 2023
In This Issue
New Mitochondrial Disease Identified In Monozygotic Twin Boys
Prolidase deficiency: A novel <scp><i>PEPD</i></scp> missense variant in exon 2
<scp><i>LYRM7</i>‐associated</scp> mitochondrial complex <scp>III</scp> deficiency with n<scp>on‐cavitating</scp> leukoencephalopathy and s<scp>troke‐like</scp> episodes
Marked intrafamilial variability of clinical and neuroimaging manifestations in <i>NFIB</i>‐related developmental disorder
<scp><i>ARID2</i></scp>, a rare cause of <scp>Coffin‐Siris</scp> syndrome: A novel microdeletion at 12q12q13.11 causing severe short stature and literature review
Eighth case of <scp>Li‐Campeau</scp> syndrome in a Turkish patient caused by a novel pathogenic variant in <i>UBR7</i> and expanding the phenotype
Systemic artery to pulmonary artery aneurysm malformations associated with variants at <i>MCF2L</i>
A mutational hotspot in <scp><i>AMOTL1</i></scp> defines a new syndrome of orofacial clefting, cardiac anomalies, and tall stature
Phenotypic heterogeneity in 22q11.2 deletion syndrome: <scp>Copy Number Variants</scp> as genetic modifiers for congenital heart disease in a Brazilian cohort
Clinical findings in 39 individuals with <scp>Bohring–Opitz</scp> syndrome from a global patient‐driven registry with implications for tumor surveillance and recurrence risk
Time course of serum neuron‐specific enolase levels from infancy to early adulthood in a female patient with beta‐propeller protein‐associated neurodegeneration
Novel phenotype of aortic root dilatation and late‐onset metabolic decompensation in a patient with <i>TMEM70</i> deficiency
First implication of <scp><i>MIP</i></scp> in bilateral microphthalmia with persistent fetal vasculature
Further delineation of the <scp><i>CWC27</i>‐associated</scp> spliceosomeopathy: Case report and review of the literature
Tethered cord syndrome in <scp>KBG</scp> syndrome
The past, present, and future of child growth monitoring: A review and primer for clinical genetics
Novel noncanonical splice site variant causes mild <scp><i>CHD7</i></scp>‐related disorder with variable intrafamilial expressivity
Genetic testing in the evaluation of individuals with clinical diagnosis of atypical<scp>Sturge–Weber</scp>syndrome
An automatic facial landmarking for children with rare diseases
<i>PPM1K</i> defects cause mild maple syrup urine disease: The second case in the literature
A homozygous truncating <scp><i>ETV4</i></scp> variant in a Nigerian family with congenital anomalies of the kidney and urinary tract
Mosaic pathogenic variants in <scp><i>AKT3</i></scp> cause capillary malformation and undergrowth
Periventricular heterotopia in a male child with <scp><i>USP9X</i></scp> missense variant
Insights into the perinatal phenotype of Kabuki syndrome in infants identified by genome‐wide sequencing
The spectrum of neurological manifestations and genotype–phenotype correlation in Indian children with Gaucher disease Indian children; in India
A pilot study of home‐based genetic testing completion rate in telegenetics cancer clinics in West Virginia Appalachia
Deletion of first noncoding exon in <i>ANKRD11</i> leads to <scp>KBG</scp> syndrome
A novel biallelic <scp><i>CRIPT</i></scp> variant in a patient with short stature, microcephaly, and distinctive facial features
Genomic sequencing in a cohort of individuals with fibular aplasia, tibial campomelia, and oligosyndactyly (FATCO) syndrome
Response to Letter to the Editor by Palffy and Ghaziuddin
Addressing the Weaponization of Genetic Research
In This Issue
Table of Contents, Volume 191A, Number 2 February 2023
Evidence Grows for Universal Germline Genetic Testing for Patients with Breast Cancer
Publication schedule for 2023
Delineating the phenotype of <i>RNU4ATAC</i>‐related spliceosomopathy
Neonatal diagnosis of <scp>ACTA2</scp>‐related disease: A case report and review of literature
Neuropsychological and mental health concerns in a multicenter clinical sample of youth with turner syndrome
Next generation phenotyping with quantitative narration for DEGCAGS syndrome
Seizures in trisomy 18: Prevalence, description, and treatment
Letter to the Editor regarding “Unexplained regression in Down syndrome: Management of 51 patients in an international patient database” by Santoro et al.
A biallelic frameshift indel in <i>PPP1R35</i> as a cause of primary microcephaly Turkish; Iranian; predominantly Iranian families; consanguineous Turkish kindred; genetic background
Mosaic genome‐wide paternal uniparental disomy after discordant results from primary fetal samples and cultured cells
Concurrent de novo <scp>ZFHX4</scp> variant and 16q24.1 deletion in a patient with orofacial clefting; a potential role of <scp>ZFHX4</scp> and <scp>USP10</scp>
Novel <scp><i>CRB1</i></scp> pathogenic variant in <scp>Chuuk</scp> families with <scp>Leber</scp> congenital amaurosis
Investigation of a pervasive immune, cardiac, and behavioral phenotype in <scp>Beckwith‐Wiedemann</scp> syndrome: A case report